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Bart-Pumphrey syndrome
ICD-10 Codes
Related ICD-10:
Description
Bart-Pumphrey syndrome, also known as knuckle pads, leukonychia, and sensorineural deafness, is a rare autosomal dominant disorder characterized by several distinct physical and auditory features.
Physical Features:
- Knuckle Pads: A common feature of Bart-Pumphrey syndrome is the presence of thickened skin on the palmar surfaces of the hands, known as knuckle pads.
- Leukonychia: People with this condition often have white or opaque patches on their nails, a condition known as leukonychia.
- Palmoplantar Keratoderma: Thickening of the skin on the palms and soles is also a characteristic feature.
Auditory Features:
- Sensorineural Hearing Loss: The most constant feature of Bart-Pumphrey syndrome is congenital, mild to severe sensorineural hearing loss, caused by a cochlear defect. This can range from mild hearing impairment to profound deafness.
These physical and auditory features are the hallmarks of Bart-Pumphrey syndrome, making it a unique condition among other genetic disorders.
References:
- [2] Bart-Pumphrey syndrome (OMIM 149200), also known as knuckle pads, leukonychia, and sensorineural deafness, is a rare autosomal-dominant syndrome.
- [4] Bart-Pumphrey syndrome (BPS) is an autosomal-dominant disorder characterized by hearing loss, leukonychia, knuckle pads and palmoplantar keratoderma.
- [6] Mar 24, 2022 — Bart-Pumphrey syndrome (BPS), also known as knuckle pads, leukonychia, and sensorineural deafness, is a rare autosomal dominant disorder ...
- [9] by G Richard · 2004 · Cited by 125 — Bart–Pumphrey syndrome (BPS) is an autosomal dominant disorder characterized by sensorineural hearing loss, palmoplantar keratoderma, knuckle pads, and ...
Additional Characteristics
- Sensorineural Hearing Loss
- Knuckle Pads
- Leukonychia
- Palmoplantar Keratoderma
Signs and Symptoms
Bart-Pumphrey syndrome is a rare genetic disorder characterized by several distinct signs and symptoms.
Main Features:
- Nail abnormalities: People with Bart-Pumphrey syndrome typically have white or opaque nails, known as leukonychia [1][2][5].
- Skin abnormalities: The condition is also associated with skin findings, including knuckle pads (hardened areas on the joints of the fingers and toes) [4][6], palmoplantar keratoderma (thickening of the skin on the palms and soles), and other skin lesions.
- Hearing loss: Congenital or early-onset sensorineural hearing loss is a constant feature of this disorder, caused by a cochlear defect [8][9].
Other Possible Features:
- Symmetric or asymmetric knuckle pads, typically located on the distal and interphalangeal joints [6]
- Palmoplantar keratoderma (PPK) [4]
It's essential to note that Bart-Pumphrey syndrome is a rare condition, and not all individuals with this disorder will exhibit all
Additional Symptoms
- Nail abnormalities: white or opaque nails
- Skin abnormalities: knuckle pads, palmoplantar keratoderma, other skin lesions
- Hearing loss: congenital or early-onset sensorineural hearing loss
- Symmetric or asymmetric knuckle pads on distal and interphalangeal joints
- Palmoplantar keratoderma (PPK)
Diagnostic Tests
Bart-Pumphrey syndrome, also known as knuckle pads, leukonychia, and sensorineural deafness, is a rare autosomal-dominant syndrome characterized by nail and skin abnormalities and hearing loss.
Diagnostic tests for Bart-Pumphrey syndrome:
- Mutation scanning/screening: This test involves analyzing the genetic material to identify mutations associated with Bart-Pumphrey syndrome. It can be performed using Next-Generation Sequencing (NGS) sequencing, except Whole Exome Sequencing (WES), or Sanger sequencing of selected exons [2][4].
- Deletion/duplication analysis: This test is used to detect deletions or duplications in the genetic material that may be associated with Bart-Pumphrey syndrome [5].
- Microsatellite instability testing (MSI): This test is used to assess the stability of microsatellites, which are short DNA sequences that repeat multiple times. MSI can help identify mutations associated with Bart-Pumphrey syndrome [5].
- Targeted variant analysis: This test involves analyzing specific genetic variants associated with Bart-Pumphrey syndrome [5].
Clinical Genetic Tests:
- Fulgent Genetics: Offers a Clinical Genetic Test for conditions, including Bart-Pumphrey syndrome. The test includes mutation scanning/screening and sequence analysis of selected exons [7].
- IVAMI: Performs detection of mutations associated with Bart-Pumphrey syndrome by complete PCR amplification of exons GJB2, followed by sequencing [9].
Other Diagnostic Tests:
- Diagnostic sonography: This is a type of real-time imaging technology that uses high-frequency sound waves to process images and movement from within the body. It can be used in conjunction with other diagnostic tests to help diagnose Bart-Pumphrey syndrome [14].
- Imaging services: Various imaging services, such as MRI scans, CT scans, X-rays, ultrasounds & screening mammograms, may also be used to support diagnosis [10][11][12][13].
Please note that these diagnostic tests are not exhaustive and may vary depending
Additional Diagnostic Tests
- Targeted variant analysis
- duplication analysis
- screening
- Microsatellite instability testing (MSI)
- Diagnostic sonography
- Imaging services
Treatment
Bart-Pumphrey syndrome is a rare genetic disorder characterized by nail and skin abnormalities, hearing loss, and knuckle pads. While there is no cure for the condition, various treatments can help manage its symptoms.
Treatment Options:
- Steroid injections: Injecting steroid medicines into the knuckle pads can shrink them, making them less noticeable [4].
- Regular hydration and skin care: Maintaining good skin health through regular hydration and proper skin care is essential for managing palmoplantar keratoderma, a common feature of Bart-Pumphrey syndrome [9].
Other Considerations:
- Molecular studies: While expensive, molecular studies can help accurately classify the condition and provide valuable information for treatment planning [9].
- Consulting a healthcare professional: It is essential to consult with a healthcare professional for personalized medical advice and treatment. They can help determine the best course of action based on individual needs.
Important Note:
- Bart-Pumphrey syndrome is a rare and complex condition, and its treatment may vary depending on individual circumstances. Consultation with a healthcare professional is crucial for accurate diagnosis and effective management.
References:
[4] - Steroid injections can shrink knuckle pads, making them less noticeable. [9] - Regular hydration and skin care remains primary therapy; molecular studies are imperative for accurate classification.
Recommended Medications
- Regular hydration and skin care
- steroid
💊 Drug information is sourced from ChEBI (Chemical Entities of Biological Interest) database. Always consult with a healthcare professional before starting any medication. Click on any medication name for detailed information.
Differential Diagnosis
Bart-Pumphrey syndrome (BPS) is a rare genetic disorder characterized by sensorineural hearing loss, palmoplantar keratoderma, knuckle pads, and leukonychia. When attempting to diagnose BPS, it's essential to consider differential diagnoses that
Additional Differential Diagnoses
- Vohwinkel syndrome
- Palmoplantar keratoderma with spastic paraplegia
- Keratitis ichthyosis deafness (KID) syndrome
- Ectodermal dysplasias
Additional Information
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- https://w3id.org/def/predibionto#has_symptom_695
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- MIM:149200
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- A syndrome that is characterized by leukonychia, wart-like skin growths, palmoplantar keratoderma and hearing loss, has_material_basis_in heterozygous mutation in the GJB2 gene on chromosome 13q12.
- oboInOwl#hasExactSynonym
- KNUCKLE PADS, LEUKONYCHIA, AND SENSORINEURAL DEAFNESS
- IDO_0000664
- http://purl.obolibrary.org/obo/GENO_0000147
- rdf-schema#comment
- OMIM mapping confirmed by DO. [SN].
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It is not intended to be a substitute for professional medical advice, diagnosis, or treatment. Always seek the advice of your physician or other qualified healthcare provider with questions about your medical condition.